Exon-scanning mutation analysis of the ATM gene in patients with ataxia-telangiectasia

被引:0
|
作者
Vorechovsky, I
Luo, LP
Prudente, S
Chessa, L
Russo, G
Kanariou, M
James, M
Negrini, M
Webster, ADB
Hammarstrom, L
机构
[1] ROYAL FREE HOSP,SCH MED,DEPT CLIN IMMUNOL,LONDON,ENGLAND
[2] UNIV ROMA LA SAPIENZA,DEPT METAB DISORDERS,ROME,ITALY
[3] RAGGIO ITALGENE,GENET MOL LAB,POMEZIA,ITALY
[4] AGHIA SOPHIA CHILDRENS HOSP,DEPT IMMUNOL & HISTOCOMPATIBIL,ATHENS,GREECE
[5] UNIV OXFORD,WELLCOME TRUST CTR HUMAN GENET,OXFORD OX1 2JD,ENGLAND
[6] THOMAS JEFFERSON UNIV,KIMMEL CANC CTR,PHILADELPHIA,PA 19107
关键词
ataxia-telangiectasia; mutation; ATM; chromosome; 11;
D O I
暂无
中图分类号
Q5 [生物化学]; Q7 [分子生物学];
学科分类号
071010 ; 081704 ;
摘要
Using a polymerase chain reaction single strand conformation polymorphism (PCR-SSCP) assay, which amplifies individually all coding exons of the ATM gene deficient ataxia-telangiectasia (A-T), we have analyzed 10 patients with A-T for ATM mutations. Mutation were detected in 9 patients. We describe the first ATM mutation in the splice junction found in the 5' splice site of intron 17, leading to exon skipping. However, most mutations were small deletions or insertions resulting in premature termination of the translation product. The development of DNA-based methods for detection of unknown mutations and further characterization of ATM mutation pattern will facilitate identification of A-T carriers and assessment of their cancer risk.
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页码:352 / 355
页数:4
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