Nineteen-year follow-up of a patient with severe glutathione synthetase deficiency

被引:8
|
作者
Atwal, Paldeep S. [1 ,2 ]
Medina, Casey R. [1 ]
Burrage, Lindsay C. [1 ]
Sutton, V. Reid [1 ]
机构
[1] Baylor Coll Med, Dept Mol & Human Genet, One Bayor Plaza, Houston, TX 77030 USA
[2] Mayo Clin, Dept Clin Genom, Ctr Individualized Med, Jacksonville, FL USA
基金
美国国家卫生研究院;
关键词
VITAMIN-E; DIAGNOSIS;
D O I
10.1038/jhg.2016.20
中图分类号
Q3 [遗传学];
学科分类号
071007 ; 090102 ;
摘要
Glutathione synthetase deficiency is a rare autosomal recessive disorder resulting in low levels of glutathione and an increased susceptibility to oxidative stress. Patients with glutathione synthetase deficiency typically present in the neonatal period with hemolytic anemia, metabolic acidosis and neurological impairment. Lifelong treatment with antioxidants has been recommended in an attempt to prevent morbidity and mortality associated with the disorder. Here, we present a 19-year-old female who was diagnosed with glutathione synthetase deficiency shortly after birth and who has been closely followed in our metabolic clinic. Despite an initial severe presentation, she has had normal intellectual development and few complications of her disorder with a treatment regimen that includes polycitra (citric acid, potassium citrate and sodium citrate), vitamin C, vitamin E and selenium.
引用
收藏
页码:669 / 672
页数:4
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