Germline mutations of the LKB1 (STK11) gene in Peutz-Jeghers patients

被引:0
|
作者
Wang, ZJ
Churchman, M
Avizienyte, E
McKeown, C
Davies, S
Evans, DGR
Ferguson, A
Ellis, I
Xu, WH
Yan, ZY
Aaltonen, LA
Tomlinson, IPM [1 ]
机构
[1] Univ Oxford, John Radcliffe Hosp, Tumour Genet Grp, Dept Clin Med, Oxford OX3 9DU, England
[2] Beijing Univ Med, Sch Med 1, Dept Surg, Beijing, Peoples R China
[3] Univ Helsinki, Haartman Inst, Dept Med Genet, FIN-00014 Helsinki, Finland
[4] Birmingham Womens Hosp, Dept Clin Genet, Birmingham B15 2TG, W Midlands, England
[5] Univ Wales Hosp, Inst Med Genet, Cardiff CF4 4XN, S Glam, Wales
[6] St Marys Hosp, Dept Clin Genet, Manchester M13 0JH, Lancs, England
[7] Western Gen Hosp, Dept Gastroenterol, Edinburgh EH4 2XU, Midlothian, Scotland
[8] Royal Liverpool Childrens Hosp, Dept Clin Genet, Liverpool L12 2AP, Merseyside, England
[9] Imperial Canc Res Fund, Mol & Populat Genet Lab, London WC2A 3PX, England
关键词
Peutz-Jeghers syndrome; LKB1/STK11;
D O I
暂无
中图分类号
Q3 [遗传学];
学科分类号
071007 ; 090102 ;
摘要
Germline mutations of the LKB1 (STK11) serine/threonine kinase gene (chromosome 19p13.3) cause Peutz-Jeghers syndrome, which is characterised by hamartomas of the gastrointestinal tract and typical pigmentation. Peutz-Jeghers syndrome carries an overall risk of cancer that may be up to 20 times that of the general population. Here, we report the results of a screen for germline LKB1 mutations by DNA sequencing in 12 Peutz-Jeghers patients (three sporadic and nine familial cases). Mutations were found in seven (58%) cases, in exons 1, 2, 4, 6, and 9. Five of these mutations, two of which are identical, are predicted to lead to a truncated protein (three frameshifts, two nonsense changes). A further mutation is an in frame deletion of 6 bp, resulting in a deletion of lysine and asparagine; the second of these amino acids is conserved between species. The seventh mutation is a missense change in exon 2, converting lysine to arginine, affecting non-conserved amino acids and of uncertain functional significance. Despite the fact that Peutz-Jeghers syndrome is usually an early onset disease with characteristic clinical features, predictive and diagnostic testing for LKB1 mutations will be useful for selected patients in both familial and non-familial contexts.
引用
收藏
页码:365 / 368
页数:4
相关论文
共 50 条
  • [41] Two variants in STK11 gene in Chinese patients with Peutz-Jeghers syndrome
    Liu, Dan
    Guo, Hong
    Xu, Xueqing
    Yu, Yanyan
    Bai, Yun
    JOURNAL OF GENETICS, 2012, 91 (02) : 205 - 208
  • [42] Further observations on LKB1/STK11 status and cancer risk in Peutz–Jeghers syndrome
    W Lim
    N Hearle
    B Shah
    V Murday
    S V Hodgson
    A Lucassen
    D Eccles
    I Talbot
    K Neale
    A G Lim
    J O'Donohue
    A Donaldson
    R C Macdonald
    I D Young
    M H Robinson
    P W R Lee
    B J Stoodley
    I Tomlinson
    D Alderson
    A G Holbrook
    S Vyas
    E T Swarbrick
    A A M Lewis
    R K S Phillips
    R S Houlston
    British Journal of Cancer, 2003, 89 : 308 - 313
  • [43] Clinical characteristics and STK11 gene mutations in Chinese children with Peutz-Jeghers syndrome
    Zhiheng Huang
    Shijian Miao
    Lin Wang
    Ping Zhang
    Bingbing Wu
    Jie Wu
    Ying Huang
    BMC Gastroenterology, 15
  • [44] Genomic deletions and point mutations in the STK11 gene in Peutz-Jeghers Chilean families
    Orellana, Paulina
    Alvarez, Karin
    Heine, Claudio
    Suazo, Cristobal
    Pinto, Eliana
    Carvallo, Pilar
    Lopez-Kostner, Francisco
    CANCER RESEARCH, 2012, 72
  • [45] Clinical characteristics and STK11 gene mutations in Chinese children with Peutz-Jeghers syndrome
    Huang, Zhiheng
    Miao, Shijian
    Wang, Lin
    Zhang, Ping
    Wu, Bingbing
    Wu, Jie
    Huang, Ying
    BMC GASTROENTEROLOGY, 2015, 15
  • [46] Novel and Recurrent Mutations of STK11 Gene in Six Chinese Cases with Peutz-Jeghers Syndrome
    Dai, Limeng
    Fu, Liyuan
    Liu, Dan
    Zhang, Kun
    Wu, Yuanyuan
    Meng, Hui
    Zhang, Bo
    Guan, Xingying
    Guo, Hong
    Bai, Yun
    DIGESTIVE DISEASES AND SCIENCES, 2014, 59 (08) : 1856 - 1861
  • [47] Analysis of STK11 Gene Variant in Five Chinese Patients with Peutz-Jeghers Syndrome
    BiXia Zheng
    Jian Pan
    Yaping Wang
    Mei Li
    Min Lian
    Yucan Zheng
    Yu Jin
    Digestive Diseases and Sciences, 2013, 58 : 2868 - 2872
  • [48] Two novel LKB1 mutations in Colombian Peutz-Jeghers syndrome patients
    Velez, A.
    Gaitan, M. H.
    Marquez, J. R.
    Castano, A.
    Restrepo, J. I.
    Jaramillo, S.
    Gamarra, A.
    Novelli, M.
    Echeverry, M. M.
    Tomlinson, I.
    Carvajal-Carmona, L. G.
    CLINICAL GENETICS, 2009, 75 (03) : 304 - 306
  • [49] A novel mutation in STK11 gene is associated with Peutz-Jeghers Syndrome in Chinese patients
    Wang, Zhiqing
    Chen, Yulan
    Wu, Baoping
    Zheng, Haoxuan
    He, Jiman
    Jiang, Bo
    BMC MEDICAL GENETICS, 2011, 12
  • [50] Analysis of STK11 Gene Variant in Five Chinese Patients with Peutz-Jeghers Syndrome
    Zheng, BiXia
    Pan, Jian
    Wang, Yaping
    Li, Mei
    Lian, Min
    Zheng, Yucan
    Jin, Yu
    DIGESTIVE DISEASES AND SCIENCES, 2013, 58 (10) : 2868 - 2872