Case report: Experience of a rare case of rebound of the Kasabach-Merritt phenomenon during sirolimus treatment in kaposiform hemangioendothelioma

被引：1
|
作者：
Wang, Liang [1 ]
Li, Jing [1 ]
Wu, Changhua [1 ]
Song, Dan [1 ]
Liu, Zhuang [1 ]
Niu, Yanli [1 ]
Zhou, Jie [1 ]
Guo, Lei [1 ,2 ,3 ]
机构：
[1] Shandong Univ, Childrens Hosp, Dept Vasc Anomalies & Intervent Radiol, Jinan, Peoples R China
[2] Jinan Childrens Hosp, Dept Vasc Anomalies & Intervent Radiol, Jinan, Peoples R China
[3] Shandong Prov Clin Res Ctr Childrens Hlth & Dis, Jinan, Peoples R China
来源：
FRONTIERS IN PEDIATRICS | 2022年 / 10卷
关键词：
kaposiform hemangioendothelioma; Kasabach-Merritt phenomenon; embolization; ablation; vincristine; prognosis;
D O I：
10.3389/fped.2022.949950
中图分类号：
R72 [儿科学];
学科分类号：
100202 ;
摘要：
Kaposiform hemangioendothelioma (KHE) is a rare vascular neoplasm associated with the Kasabach-Merritt phenomenon (KMP), which is a consumptive coagulopathy with associated potentially life-threatening thrombocytopenia. There are no standardized treatment protocols for the management of KHE with KMP. Moreover, there are limited reports regarding the treatment of cases of rebound. Herein, we describe a rare case of rebound of KHE/KMP, during systemic sirolimus treatment, successfully treated with embolization and vincristine infusion combined with microwave ablation.
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页数：5
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