Understanding primary ciliary dyskinesia

被引:0
|
作者
Ferkol, Thomas [1 ]
机构
[1] Univ N Carolina, Sch Med, Dept Pediat, Chapel Hill, NC USA
基金
美国国家卫生研究院;
关键词
airway; bronchiectasis; cilia; ciliopathies; heterotaxy; infection; inflammation; situs inversus totalis;
D O I
10.1002/ppul.27360
中图分类号
R72 [儿科学];
学科分类号
100202 ;
摘要
Primary ciliary dyskinesia (PCD) is a rare, inherited disease characterized by impaired motile ciliary function leading to chronic sinopulmonary disease, persistent middle ear effusions, laterality defects, and subfertility. Over fifty PCD-associated genes have also been identified, which have provided new insights into the processes involved into ciliary assembly, structure, and function. Historically, the diagnosis of PCD was based on the presence of ultrastructural defects in the ciliary axoneme but with identification of a growing number of disease-associated genes, genetic testing has become a first-line diagnostic tool. Other approaches have also evolved, that have improved our diagnostic capabilities. Treatments for PCD have lagged, and though our growing understanding of the genetic and pathophysiological bases of the disease of PCD may yield to better therapeutic strategies.
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页数:2
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